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Immunologically Mediated Skin Diseases

Chapter 62 | Part 2: Cardinal Manifestations and Presentation of Diseases

KEY CLINICAL POINTS

  • Immunologically mediated skin diseases are autoimmune disorders with cutaneous manifestations, characterized by blistering, erosions, and scarring.
  • Key diagnostic tools include direct immunofluorescence microscopy, histopathology, and detection of autoantibodies (e.g., IgG, IgA) against desmosomal proteins (Dsg1, Dsg3, BPAG1, BPAG2).
  • Treatment varies by disease: glucocorticoids, immunosuppressants (e.g., rituximab, mycophenolate mofetil), dapsone for dermatitis herpetiformis, and strict gluten-free diets for DH.
  • Differential diagnosis includes vasculitis, infections (e.g., Meleney’s ulcer), and drug reactions (e.g., DRESS syndrome).
  • Prognosis depends on disease severity, response to treatment, and complications (e.g., ocular involvement in pemphigoid gestationis).

1. DEFINITION & OVERVIEW

Immunologically mediated skin diseases are autoimmune disorders characterized by blistering, erosions, and scarring. These conditions involve autoantibodies targeting desmosomal proteins (e.g., Dsg1, Dsg3) or basement membrane antigens (e.g., BPAG1, BPAG2). Clinically, they present with mucocutaneous lesions, pruritus, and disfigurement, with potential complications including secondary infections and systemic involvement.

Table 62-1: Immunologically Mediated Blistering Diseases

DISEASE CLINICAL MANIFESTATIONS HISTOLOGY IMMUNOPATHOLO GY AUTOANTIGENS
Pemphigus vulgaris Oromucosal lesions, flaccid blisters, denuded skin Acantholytic blister formed in suprabasal layer of epidermis Cell surface deposits of IgG on keratinocytes Dsg3 (plus Dsg1 in patients with skin involvement)
Pemphigus foliaceus Crusts and shallow erosions on scalp, central face, upper chest, and back Acantholytic blister formed in superficial layer of epidermis Cell surface deposits of IgG on keratin,ocytes Dsg1
Paraneoplastic pemphigus Painful stomatitis with papulosquamous or lichenoid eruptions progressing to blisters Acantholysis, keratinocyte necrosis, vacuolar interface dermatitis Cell surface deposits of IgG and C3 on keratinocytes Plakin protein family members and desmosomal cadherins
DISEASE CLINICAL MANIFESTATIONS HISTOLOGY IMMUNOPATHOLO GY AUTOANTIGENS
Bullous pemphigoid Large tense blisters on flexor surfaces and trunk Subepidermal blister with eosinophil-rich infiltrate Linear band of IgG and/or C3 in epidermal BMZ BPAG1, BPAG2
Pemphigoid gestationis Pruritic, urticarial plaques rimmed by vesicles and bullae on trunk and extremities Teardrop-shaped, subepidermal blisters in dermal papillae Linear band of C3 in epidermal BMZ BPAG2 (plus BPAG1 in some patients)
Dermatitis herpetiformis Extremely pruritic small papules and vesicles on elbows, knees, buttocks, and posterior neck Subepidermal blister with neutrophils in dermal papillae Granular deposits of IgA in dermal papillae Epidermal transglutaminase
Linear IgA disease Pruritic papulovesicles on extensor surfaces; occasionally larger, arciform blisters Subepidermal blister with neutrophil-rich infiltrate Linear band of IgA in epidermal BMZ BPAG2
Epidermolysis bullosa acquisita Blisters, erosions, scars, and milia on trauma-exposed sites Subepidermal blister with or without leukocytic infiltrate Linear band of IgG and/or C3 in epidermal BMZ Type VII collagen
Mucous membrane pemphigoid Erosive and/or blistering lesions of mucous membranes and skin Subepidermal blister with or without leukocytic infiltrate Linear band of IgG, IgA, and/or C3 in epidermal BMZ BPAG2, laminin-332, or others

1.1 Classification

Diseases are categorized into blistering disorders (e.g., pemphigus, bullous pemphigoid), non-blistering (e.g., dermatitis herpetiformis), and those with subepidermal or intraepidermal blistering. Autoantibodies target specific antigens, leading to acantholysis or subepidermal blistering.

1.2 Pathogenesis

Autoantibodies (IgG, IgA) bind to desmosomal or basement membrane antigens, triggering complement activation, neutrophil infiltration, and tissue damage. HLA associations (e.g., HLA-DQ β 1*0301, HLA-B8/DRw3) influence disease susceptibility.

2. EPIDEMIOLOGY

Pemphigus vulgaris (PV) is most common in adults >40 years, with a prevalence of 1–2/100,000. Bullous pemphigoid (BP) peaks in elderly (60–80 years), with a prevalence of 10–20/100,000. Dermatitis herpetiformis (DH) is more common in adults, with a prevalence of 1–2/100,000. Pemphigoid gestationis (PG) occurs in 1–2/100,000 pregnancies. Risk factors include autoimmune diseases (e.g., inflammatory bowel disease, rheumatoid arthritis), medications (e.g., penicillamine, diuretics), and HLA associations (e.g., HLA-DQ β 1*0301 for BP).

2.1 Demographics

PV: >40 years; BP: elderly (60–80 years); DH: adults; PG: women of childbearing age; MMP: rare, no gender predilection.

2.2 Risk Factors

Autoimmune diseases (e.g., IBD, RA), medications (e.g., thiol-containing drugs, diuretics), HLA associations (e.g., HLA-B8/DRw3 for DH), and genetic predisposition.

3. ETIOLOGY & PATHOPHYSIOLOGY

Autoantibodies target desmosomal proteins (Dsg1, Dsg3) or basement membrane antigens (BPAG1, BPAG2). Complement activation, neutrophil infiltration, and cytokine release mediate tissue damage. HLA associations (e.g., HLA-DQ β 1*0301 for BP, HLA-B8/DRw3 for DH) influence disease susceptibility. Paraneoplastic pemphigus (PNP) is linked to neoplasms (e.g., lymphoma, thymoma).

3.1 Autoimmune Mechanisms

IgG autoantibodies bind to desmosomal proteins (Dsg1, Dsg3) or basement membrane antigens (BPAG1, BPAG2), causing acantholysis or subepidermal blistering. Complement activation and neutrophil infiltration exacerbate tissue damage.

3.2 HLA Associations

HLA-DQ β 10301 (BP), HLA-B8/DRw3 (DH), HLA-DR2 (EBA), and HLA-DQ β 10301 (PNP) are linked to disease susceptibility.

4. CLINICAL FEATURES

PV presents with flaccid blisters, mucosal erosions, and scarring. BP features tense blisters on flexor surfaces. DH has pruritic papules on extensor surfaces. PG causes pruritic plaques on abdomen and extremities. MMP involves mucous membranes (e.g., oral, conjunctival). EBA is a mechanobullous disease with blisters at trauma sites.

4.1 Pemphigus Vulgaris

Flaccid blisters, mucosal erosions, scarring. Lesions on oral mucosa are almost invariable. Severe cases may lead to secondary infections and systemic complications.

4.2 Bullous Pemphigoid

Tense blisters on flexor surfaces and trunk. Pruritus is prominent. Lesions may rupture to form erosions with crusts. Nontraumatized blisters heal without scarring.

4.3 Dermatitis Herpetiformis

Pruritic papules on extensor surfaces (elbows, knees). Associated with gluten-sensitive enteropathy. Lesions may resemble severe seborrheic dermatitis.

5. DIFFERENTIAL DIAGNOSIS

Vasculitis, Meleney’s ulcer (infection), cutaneous leishmaniasis, drug reactions (e.g., DRESS syndrome), and fungal infections (e.g., cutaneous candidiasis). Differentiate based on histopathology, immunofluorescence, and clinical context.

5.1 Infections

Meleney’s ulcer (synergistic infection), cutaneous leishmaniasis, fungal infections (e.g., dimorphic fungi, amebiasis).

5.2 Drug Reactions

DRESS syndrome, drug-induced pemphigus (e.g., penicillamine, captopril).

6. INVESTIGATIONS & DIAGNOSIS

Direct immunofluorescence (IgG, IgA, C3 in epidermal basement membrane), histopathology (acantholysis, subepidermal blisters), and autoantibody testing (ELISA, indirect immunofluorescence). Serological markers (e.g., anti-endomysial antibodies for DH) and HLA typing are also critical.

6.1 Diagnostic Tests

Direct immunofluorescence: IgG/IgA/C3 in basement membrane. Histopathology: acantholysis (PV), subepidermal blisters (BP). Autoantibody testing: ELISA for Dsg1/Dsg3, IgA for DH.

6.2 Serological Markers

Anti-endomysial antibodies (DH), anti-Ro/SSA (SCLE), and HLA typing (e.g., HLA-B8/DRw3 for DH).

7. MANAGEMENT & TREATMENT

Systemic glucocorticoids (prednisone), immunosuppressants (rituximab, mycophenolate mofetil), dapsone for DH, and strict gluten-free diets. For severe cases, IVIg or plasmapheresis may be required. Local treatments include topical corticosteroids and photoprotection.

7.1 Pharmacologic Therapy

Glucocorticoids (prednisone), rituximab, mycophenolate mofetil, azathioprine, dapsone (DH), and IVIg for refractory cases.

7.2 Non-Pharmacologic

Strict gluten-free diet for DH, photoprotection, and wound care for erosions.

8. PROGNOSIS & COMPLICATIONS

PV mortality is ~5% with treatment; BP has a better prognosis. Complications include secondary infections, ocular involvement (PG), and systemic complications (e.g., bronchiolitis obliterans in PNP). Long-term management is required for chronic conditions like DH and MMP.

8.1 Mortality

PV: ~5% with treatment; PNP: 50% mortality if neoplasm is untreated.

8.2 Complications

Secondary infections, scarring, ocular involvement (PG), and systemic complications (e.g., interstitial lung disease in dermatomyositis).

9. SPECIAL CONSIDERATIONS

Pregnancy: PG may recur in subsequent pregnancies; DH requires gluten-free diet. Pediatrics: DH in children, EBA in infants. Drug-induced pemphigus (e.g., penicillamine, diuretics).

9.1 Pregnancy

PG: recurrence in subsequent pregnancies; DH: gluten-free diet. Avoid corticosteroids in early pregnancy.

9.2 Pediatrics

DH in children, EBA in infants, and drug-induced pemphigus (e.g., thiol-containing drugs).

10. KEY POINTS & CLINICAL PEARLS

  1. Use direct immunofluorescence to differentiate blistering diseases. 2. Dapsone is first-line for DH, with strict gluten-free diet. 3. Rituximab is effective for refractory PV. 4. HLA typing aids in diagnosis (e.g., HLA-B8/DRw3 for DH). 5. Monitor for complications (e.g., ocular involvement in PG).